Endoglin haploinsufficiency reduces radiation-induced fibrosis and telangiectasia formation in mouse kidneys

Radiother Oncol. 2009 Sep;92(3):484-91. doi: 10.1016/j.radonc.2009.06.013. Epub 2009 Jul 1.

Abstract

Background and purpose: Endoglin is a transforming growth factor beta (TGF-beta) co-receptor mainly expressed in dividing endothelial cells. It regulates cell proliferation and survival and is upregulated at sites of vessel repair. Mutations in endoglin have been linked to the vascular disease hereditary hemorrhagic telangiectasia (HHT). HHT patients display dilated capillaries (telangiectasia) that are prone to rupture. Cancer patients receiving radiotherapy develop similar vascular damage in normal tissues lying in the irradiation field. If located in the mucosa, irradiation-induced telangiectasia can lead to severe bleeding. Therefore, this study was aimed at investigating the role of endoglin in radiation-induced telangiectasia formation.

Materials and methods: Kidneys of endoglin heterozygous (Eng(+/-)) or wild type mice were irradiated with 16 Gy. Mice were sacrificed after 20 weeks and changes in gene expression and protein levels were analysed.

Results: Expression of TGF-beta target genes involved in radiation-induced fibrosis and fibrosis development in the kidney decreased in Eng(+/-) compared to wild type mice. Unexpectedly, Eng(+/-) mice also displayed reduced telangiectasia formation in the irradiated kidney.

Conclusions: Endoglin plays an important role in the development of irradiation-induced normal tissue damage. Future studies will show whether interfering with endoglin functions protects tissues from late radiation toxicity.

MeSH terms

  • Animals
  • Biopsy, Needle
  • Disease Models, Animal
  • Endoglin
  • Female
  • Fibrosis / genetics
  • Fibrosis / pathology
  • Gene Expression Regulation
  • Haploidy
  • Immunohistochemistry
  • Intracellular Signaling Peptides and Proteins / genetics*
  • Kidney / pathology
  • Kidney / radiation effects*
  • Kidney Glomerulus / pathology
  • Kidney Glomerulus / radiation effects
  • Mice
  • Mice, Inbred C57BL
  • Probability
  • RNA, Messenger / analysis
  • Radiation Dosage
  • Radiation Injuries, Experimental / genetics*
  • Radiation Injuries, Experimental / metabolism
  • Radiation, Ionizing
  • Random Allocation
  • Receptors, Transforming Growth Factor beta / genetics
  • Receptors, Transforming Growth Factor beta / metabolism*
  • Reference Values
  • Reverse Transcriptase Polymerase Chain Reaction
  • Telangiectasis / genetics*
  • Telangiectasis / pathology

Substances

  • Endoglin
  • Eng protein, mouse
  • Intracellular Signaling Peptides and Proteins
  • RNA, Messenger
  • Receptors, Transforming Growth Factor beta